Background: Leydig cell tumors of the ovary a rare benign neoplasms, usually occur in postmenopausal women associated with symptoms of virilization. Only five cases of benign Leydig cell tumor have been reported in literature [1]. Case Report: Here is a case of Leydig cell tumor of ovary. A 58 yr old female referred from Endocrinology department due to a biochemical diagnosis of hyperandrogenism. Serum Testosterone levels were 5.36 ng/ml. The patient presented with alopecia and hirsutism since 12 yrs. Ultrasonography showed right ovary measuring 2.8x1.8 cm with isoechoic lesion, left ovary measuring 3.8x2.6 cm. CT scan showed subserosal fibroid measuring 3x3.6 cm in fundus of uterus both ovaries were in postmenopausal status. Hysterectomy with bilateral salpingo-oophorectomy was performed. Results: Histopathological finding revealed bilateral Leydig cell tumor, measuring 2.0x1.5 cm in the right and left ovary. After surgery serum testosterone level were in normal limits and there was regression of signs of virilization. Conclusion: Bilateral Leydig cell tumor are rare, usually benign, they require surgical treatment and followup.