Cases of condylar agenesis as such are rare and present a multipronged problem involvingdevelopment, growth and aesthetic of face as well as occlusal and dentition development problems. In the absence of any long term study and shortage of subject material, management protocol of problems associated with agenesis of condyle vary from institute to institute and there is no internationally accepted protocol for same. We are presenting a case of unilateral condylar agenesis with severe malocclusion along with its unique orthosurgical management that has never been published before. We propose to have future studies based upon our experience in this case so as to fine tune processand refine proposed treatment plan to manage adult case of unilateral condylar agenesis. Subject in discussion is a 17 year old boy with agenesis of left condyle and perfectly normal right side condyle resulting in deviation towards left side of face. Case was managed by right side vertical ramal osteotomy with advancing genioplasty along with orthodontic treatment concurrently.

Key Words: Condylar agenesis, condyle, Orthodontic treatment